HALOS: A Study to Evaluate the Safety, Tolerability, Pharmacokinetics and Pharmacodynamics of Intrathecally Administered ION582 in Patients With Angelman Syndrome

Who is this study for? Patients with Angelman syndrome
What treatments are being studied? ION582
Status: Recruiting
Location: See all (11) locations...
Intervention Type: Drug
Study Type: Interventional
Study Phase: Phase 1/Phase 2
SUMMARY

The purpose of this study is to evaluate the safety and tolerability of ascending doses of ION582 administered intrathecally in participants with Angelman syndrome.

Eligibility
Participation Requirements
Sex: All
Maximum Age: 50
Healthy Volunteers: f
View:

• Participant has a documented and certified diagnosis of Angelman syndrome (AS) (ubiquitin-protein ligase E3A \[UBE3A\] deletion or UBE3A mutation)

• Male or female between the ages of 0-50 years of age, with signed informed consent from parent(s) or legal guardian(s)

• Currently receiving stable standard of care treatments such as, stable doses of anti-epileptic medication, behavioral management medications, sleep medications, gabapentin, cannabidiol, and including special diets, supplements or nutritional support for at least 3 months prior to first dose.

• Follow good study practice and not participate in the sharing of personal or study information on social media platforms, such as any website or social media site (e.g., Facebook, Instagram, Twitter, YouTube, etc.) until notified that the study is completed.

Locations
United States
California
Rady Children's Hospital
ACTIVE_NOT_RECRUITING
San Diego
Colorado
Colorado Children's Hospital Research Institute
RECRUITING
Aurora
Illinois
Rush University Medical Center
RECRUITING
Chicago
Massachusetts
Boston Children's Hospital
RECRUITING
Boston
North Carolina
University of North Carolina at Chapel Hill School of Medicine
RECRUITING
Carrboro
Texas
Texas Children's Hospital
ACTIVE_NOT_RECRUITING
Houston
Other Locations
Australia
Sydney Children's Hospital, Kids Cancer Centre
ACTIVE_NOT_RECRUITING
Randwick
France
Necker-Enfants Malades Hospital
ACTIVE_NOT_RECRUITING
Paris
Israel
Sheba Medical Center
RECRUITING
Ramat Gan
Italy
Azienda Ospedaliera Universitaria Pisana
RECRUITING
Pisa
United Kingdom
STRONG Group University of Oxford
ACTIVE_NOT_RECRUITING
Oxford
Contact Information
Primary
Ionis Pharmaceuticals
IonisAngelmanStudy@clinicaltrialmedia.com
(844) 200-6263
Time Frame
Start Date: 2021-12-22
Estimated Completion Date: 2029-03
Participants
Target number of participants: 70
Treatments
Experimental: Part 1 MAD: Cohort A
ION582 will be administered as IT injection over a period of 13 weeks, with a minimum of approximately 4 weeks between each dose administration.
Experimental: Part 1 MAD: Cohort B
ION582 will be administered as IT injection over a period of 13 weeks, with a minimum of approximately 4 weeks between each dose administration.
Experimental: Part 1 MAD: Cohort C
ION582 will be administered as IT injection over a period of 13 weeks, with a minimum of approximately 4 weeks between each dose administration.
Experimental: Part 1 MAD: Cohort D
ION582 will be administered as IT injection over a period of 13 weeks, with a minimum of approximately 4 weeks between each dose administration.
Experimental: Part 1 MAD: Cohort E
ION582 will be administered as IT injection of over a period of 13 weeks, with a minimum of approximately 4 weeks between each dose administration.
Experimental: Part 1 MAD: Cohort F
ION582 will be administered as IT injection over a period of 13 weeks, with a minimum of approximately 12 weeks between each dose administration.
Experimental: Part 2 Group 1
ION582 will be administered as IT injection of over a period of 49 weeks, with additional dosing intervals.
Experimental: Part 2 Group 2
ION582 will be administered as IT injection of over a period of 49 weeks, with additional dosing intervals.
Experimental: Part 3 Group 1
ION582 will be administered as IT injection of over a period of 145 weeks, with additional dosing intervals.
Experimental: Part 3 Group 2
ION582 will be administered as IT injection of over a period of 145 weeks, with additional dosing intervals.
Related Therapeutic Areas
Sponsors
Leads: Ionis Pharmaceuticals, Inc.

This content was sourced from clinicaltrials.gov