The ENERGY Study: An Open-Label Study to Evaluate the Safety, Tolerability, Pharmacokinetics, and Pharmacodynamics of INZ-701 in Infants With Ectonucleotide Pyrophosphatase/ Phosphodiesterase 1 (ENPP1) Deficiency or ATP-binding Cassette Sub-family C Member 6 (ABCC6) Deficiency

Status: Recruiting
Location: See all (7) locations...
Intervention Type: Drug
Study Type: Interventional
Study Phase: Phase 1
SUMMARY

The primary purpose of Study INZ701-104 (the ENERGY study) is to assess the safety and tolerability of INZ-701 in infants with ENPP1 Deficiency or with ABCC6 Deficiency.

Eligibility
Participation Requirements
Sex: All
Maximum Age: 1
Healthy Volunteers: f
View:

• Caregiver(s) must provide written or electronic consent after the nature of the study has been explained, and prior to any research-related procedures, per International Council for Harmonisation (ICH) Good Clinical Practice (GCP)

• Study participant must have a confirmed post-natal molecular genetic diagnosis of ENPP1 Deficiency or ABCC6 Deficiency with biallelic mutations (ie, homozygous or compound heterozygous) performed by a College of American Pathologists/Clinical Laboratory Improvement Amendments (CAP/CLIA) certified laboratory

• Study participants must have clinical manifestations of GACI or GACI-2, which may include, but are not limited to, pathologic ectopic calcification, heart failure, respiratory distress, edema, cyanosis, hypertension, and cardiomegaly

• Study participant must be male or female from birth to \<1 year of age at Baseline (Day 1)

• Study participant must weigh ≥0.5 kg at the time of the first dose of INZ-701 in this study

• In the opinion of the Investigator, the study participant must be able to complete all aspects of the study

• Study participant's caregiver(s) must agree to provide access to their child's relevant medical records

Locations
United States
California
Rady Children's Hospital
RECRUITING
San Diego
Massachusetts
Boston Children's Hospital
RECRUITING
Boston
Ohio
Nationwide Children's Hospital
RECRUITING
Columbus
Pennsylvania
The Children's Hospital of Philadelphia
RECRUITING
Philadelphia
Utah
The University of Utah
RECRUITING
Salt Lake City
Other Locations
Spain
Hospital Sant Joan de Déu
NOT_YET_RECRUITING
Barcelona
United Kingdom
Royal Manchester Children's Hospital
RECRUITING
Manchester
Contact Information
Primary
Inozyme Clinical Trial Information
clinicaltrials@inozyme.com
+1 857 330 4340
Time Frame
Start Date: 2023-06-25
Estimated Completion Date: 2026-04-01
Participants
Target number of participants: 16
Treatments
Experimental: INZ-701
The first 2 study participants will receive 1 dose of 0.2 mg/kg on Day 1 and start at Dose Level A (0.2 mg/kg twice weekly) on Day 8.~The Data Review Committee (DRC) comprised of representatives of the Sponsor, the study Investigators, and a physician who is a subject matter expert not affiliated with the study or Sponsor, will review the safety data of the first study participant through Day 8. Contingent upon this review, the Sponsor will decide if additional study participants can begin receiving INZ-701.~After the second study participant completes Day 32, the DRC will perform a cumulative review of safety and PK/PD data and will make dosing recommendations, for example, modifying the dose of the ongoing study participants and/or changing the starting dose for future participants.~Dose Level A: 0.2 mg/kg twice weekly~Dose Level B: 0.6 mg/kg twice weekly~Dose Level C: 0.2 mg/kg once weekly~Dose Level D: 0.6 mg/kg once weekly~Dose Level E: 1.8 mg/kg once weekly
Sponsors
Leads: Inozyme Pharma

This content was sourced from clinicaltrials.gov

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