An Open Label Dose Escalation Study to Assess the Safety, Tolerability, and Pharmacologic Properties of High Dose Ambroxol Hydrochloride in Adult (≥ 18 Years of Age) Subjects With MPS III

Status: Recruiting
Location: See location...
Intervention Type: Drug
Study Type: Interventional
Study Phase: Phase 2/Phase 3
SUMMARY

A dose escalation study to evaluate the safety, tolerability, and pharmacologic properties of Ambroxol in adult participants with Sanfilippo disease(s) (MPS3).

Eligibility
Participation Requirements
Sex: All
Minimum Age: 18
Maximum Age: 99
Healthy Volunteers: f
View:

• IRB - approved informed consent/assent signed by subject and/or parent(s) or legal guardian(s).

• Genetically confirmed diagnosis of MPS III disease.

• Genomic DNA analysis demonstrating a homozygous or compound heterozygous pathogenic variants in SGSH (type A), NAGLU (type B), HGSNAT (type C), or GNS (type D) genes. Type E will not be studied.

• Elevated excretion of urinary GAGs and/or serum HS (if no historical data is available, screening GAGs and serum HS values will be utilized to assess inclusion criteria).

• Male or female; eighteen years of age and older, who is able to take Ambroxol Hydrochloride orally.

• Negative urine pregnancy test at screening for female subjects with child-bearing potential.

• The subject is willing to abstain from consumption of grapefruit, grapefruit juice, or grapefruit containing products for 72 hours prior to administration of the first dose of Ambroxol and for the duration of the treatment period.

Locations
United States
Virginia
Lysosomal & Rare Disorders Research & Treatment Center, Inc.
RECRUITING
Fairfax
Contact Information
Primary
Arooj Agha
aagha@ldrtc.org
571-732-4575
Backup
Lauren Noll
lnoll@ldrtc.org
571-732-4655
Time Frame
Start Date: 2024-12-01
Estimated Completion Date: 2026-06-30
Participants
Target number of participants: 10
Treatments
Experimental: Ambroxol Hydrochloride 30mg - 9mg/kg/day
Ambroxol Hydrochloride 30mg Dose escalation: Initial dose of 9mg/kg/day (or max dose 150mg TID)
Experimental: Ambroxol Hydrochloride 30mg - 18mg/kg/day
Ambroxol Hydrochloride 30mg Dose escalation: 18mg/kg/day (or max dose 300mg TID)
Experimental: Ambroxol Hydrochloride 30mg - 27mg/kg/day
Ambroxol Hydrochloride 30mg Dose escalation: 27mg/kg/day (or max dose 1350mg QD)
Sponsors
Leads: Ozlem Goker-Alpan
Collaborators: Team Sanfilippo

This content was sourced from clinicaltrials.gov